Sialodochostomy as treatment for imperforate submandibular duct: A systematic literature review and report of two cases

David Rosow, Robert F. Ward, Max M. April

Research output: Contribution to journalArticle

9 Citations (Scopus)

Abstract

Objective: To better understand the diagnosis, treatments, and outcomes of congenitally imperforate salivary ducts. Methods: A systematic literature review was performed using the following terms: imperforate submandibular duct, imperforate Wharton's duct, congenital atresia submandibular duct, congenital atresia sublingual duct, and congenital ranula. Only papers focusing on congenital floor of mouth cysts arising from imperforate salivary ducts were included. Two additional patients from our own experience are also discussed. Results: Seventeen papers published since 1950 met inclusion criteria. A total of 26 patients underwent therapy ranging from mere observation to complete excision of the cyst with the sublingual gland. Both of our 2 additional patients both underwent simple sialodochostomy (excision of the imperforate sublingual caruncle) with cyst decompression. For all 28 patients, there have been no reported recurrences, with mean follow-up of 24.8 months and median follow-up of 14.8 months. Conclusions: Congenital floor of mouth cysts arising from imperforate salivary ducts are rare, but they may mimic the appearance of a ranula. Unlike ranulas, these cysts may be safely and effectively cured by simple sialodochostomy. To date, 26 other cases have been described in the literature, and nearly all have been successfully treated with simple incision or marsupialization without recurrence. Care should be taken to exclude ranula as a diagnosis, as incomplete excision may likely result in recurrence.

Original languageEnglish
Pages (from-to)1613-1615
Number of pages3
JournalInternational Journal of Pediatric Otorhinolaryngology
Volume73
Issue number12
DOIs
StatePublished - Dec 1 2009
Externally publishedYes

Fingerprint

Ranula
Salivary Ducts
Cysts
Mouth Floor
Recurrence
Sublingual Gland
Therapeutics
Decompression
Observation

Keywords

  • Congenital ranula
  • Congenital salivary duct atresia
  • Imperforate submandibular duct
  • Sialodochostomy
  • Sublingual duct
  • Wharton's duct

ASJC Scopus subject areas

  • Otorhinolaryngology
  • Pediatrics, Perinatology, and Child Health

Cite this

Sialodochostomy as treatment for imperforate submandibular duct : A systematic literature review and report of two cases. / Rosow, David; Ward, Robert F.; April, Max M.

In: International Journal of Pediatric Otorhinolaryngology, Vol. 73, No. 12, 01.12.2009, p. 1613-1615.

Research output: Contribution to journalArticle

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